Charcot-Marie-Tooth disease masquerading as acute demyelinating encephalomyelitis-like illness.
نویسندگان
چکیده
X-linked Charcot-Marie-Tooth disease (CMTX1) is a clinically heterogeneous hereditary motor and sensory neuropathy with X-linked transmission. Common clinical manifestations of CMTX1 disease, as in other forms of Charcot-Marie-Tooth (CMT) disease, are distal muscle wasting and weakness, hyporeflexia, distal sensory disturbance, and foot deformities. Mutations in the connexin-32 gene (gap junction protein β1 [GJB1]) are responsible for CMTX1 disease. In this report, we describe a patient with CMTX1 disease presenting with recurrent attacks of transient and episodic acute demyelinating encephalomyelitis (ADEM)-like symptoms without previous signs of lower extremity weakness or foot deformities; the patient, as well as his asymptomatic mother, exhibited a novel GJB1 mutation (p.Met1Ile). Differential diagnosis of recurrent and transient ADEM-like illness, if unexplained, should include the possibility of CMTX1 disease.
منابع مشابه
X-linked Charcot–Marie–Tooth disease with GJB1 mutation presenting as acute disseminated encephalomyelitis-like illness
RATIONALE Charcot-Marie-Tooth disease (CMT) is typically an autosomal dominant, inherited neuropathy, although there is a rare male X-linked CMT. Such patients show central nervous system (CNS) involvement in addition to peripheral neuropathy. Recently, we encountered a patient who presented with acute disseminated encephalomyelitis (ADEM)-like symptoms, but was later diagnosed as having X-link...
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X-linked Charcot-Marie-Tooth disease (CMTX) is the second most common form of inherited demyelinating neuropathy, next to CMT type 1A, which is caused by duplication of the PMP22 gene.1 CMTX is caused by mutations in GJB1, the gene encoding connexin32 (Cx32), which belongs to a highly conserved family of proteins that form gap junctions in vertebrates. Myelinating Schwann cells express Cx32, wh...
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ورودعنوان ژورنال:
- Pediatrics
دوره 134 1 شماره
صفحات -
تاریخ انتشار 2014